Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population

An unusually high frequency of the lamellar ichthyosis TGM1 mutation, c.1187G > A, has been observed in the Ecuadorian province of Manabi. Recently, the same mutation has been detected in a Galician patient (Northwest of Spain). By analyzing patterns of genetic variation around this mutation in E...

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Autores: Esperón Moldes, Uxía Saraiva, Pardo Seco, Jacobo José, Montalván-Suárez, M., Fachal Vilar, Laura, Ginarte Val, Manuel Javier, Rodríguez Pazos, Laura, Gómez Carballa, Alberto, Moscoso, F., Ugalde-Noritz, N., Ordoñez Ugalde, Andrés, Tettamanti-Miranda, D., Ruiz, J. C., Salas Ellacuriaga, Antonio, Vega Gliemmo, Ana
Tipo de documento: artigo
Data de publicação:2019
País:España
Recursos:Servizo Galego de Saúde (SERGAS)
Repositório:RUNA. Repositorio da Consellería de Sanidade e Sergas
OAI Identifier:oai:runa.sergas.gal:20.500.11940/15761
Acesso em linha:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6509209/pdf/41598_2019_Article_43133.pdf
https://www.ncbi.nlm.nih.gov/pubmed/31073126
http://hdl.handle.net/20.500.11940/15761
Access Level:Acceso aberto
Palavra-chave:Humans
Transglutaminases
Ichthyosis
Haplotypes
Principal Component Analysis
Tandem Repeat Sequences
Genotype
transglutaminasas
genotipo
secuencias repetidas en tándem
análisis de componentes principales
humanos
haplotipos
ictiosis
FPGMX
CHUS
CHUVI
IDIS
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oai_identifier_str oai:runa.sergas.gal:20.500.11940/15761
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repository_id_str
spelling Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian populationEsperón Moldes, Uxía SaraivaPardo Seco, Jacobo JoséMontalván-Suárez, M.Fachal Vilar, LauraGinarte Val, Manuel JavierRodríguez Pazos, LauraGómez Carballa, AlbertoMoscoso, F.Ugalde-Noritz, N.Ordoñez Ugalde, AndrésTettamanti-Miranda, D.Ruiz, J. C.Salas Ellacuriaga, AntonioVega Gliemmo, AnaHumansTransglutaminasesIchthyosisHaplotypesPrincipal Component AnalysisTandem Repeat SequencesGenotypetransglutaminasasgenotiposecuencias repetidas en tándemanálisis de componentes principaleshumanoshaplotiposictiosisFPGMXCHUSCHUVIIDISAn unusually high frequency of the lamellar ichthyosis TGM1 mutation, c.1187G > A, has been observed in the Ecuadorian province of Manabi. Recently, the same mutation has been detected in a Galician patient (Northwest of Spain). By analyzing patterns of genetic variation around this mutation in Ecuadorian patients and population matched controls, we were able to estimate the age of c.1187G > A and the time to their most recent common ancestor (TMRCA) of c.1187G > A Ecuadorian carriers. While the estimated mutation age is 41 generations ago (~1,025 years ago [ya]), the TMRCA of Ecuadorian c.1187G > A carrier haplotypes dates to just 17 generations (~425 ya). Probabilistic-based inferences of local ancestry allowed us to infer a most likely European origin of a few (16% to 30%) Ecuadorian haplotypes carrying this mutation. In addition, inferences on demographic historical changes based on c.1187G > A Ecuadorian carrier haplotypes estimated an exponential population growth starting ~20 generations, compatible with a recent founder effect occurring in Manabi. Two main hypotheses can be considered for the origin of c.1187G > A: (i) the mutation could have arisen in Spain >1,000 ya (being Galicia the possible homeland) and then carried to Ecuador by Spaniards in colonial times ~400 ya, and (ii) two independent mutational events originated this mutation in Ecuador and Galicia. The geographic and cultural characteristics of Manabi could have favored a founder effect that explains the high prevalence of TGM1 c.1187G > A in this region.2019info:eu-repo/semantics/articlehttps://www.ncbi.nlm.nih.gov/pmc/articles/PMC6509209/pdf/41598_2019_Article_43133.pdfhttps://www.ncbi.nlm.nih.gov/pubmed/31073126http://hdl.handle.net/20.500.11940/15761reponame:RUNA. Repositorio da Consellería de Sanidade e Sergasinstname:Servizo Galego de Saúde (SERGAS)Ingléshttp://creativecommons.org/licenses/by/4.0/info:eu-repo/semantics/openAccessoai:runa.sergas.gal:20.500.11940/157612026-06-12T08:40:47Z
dc.title.none.fl_str_mv Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
title Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
spellingShingle Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
Esperón Moldes, Uxía Saraiva
Humans
Transglutaminases
Ichthyosis
Haplotypes
Principal Component Analysis
Tandem Repeat Sequences
Genotype
transglutaminasas
genotipo
secuencias repetidas en tándem
análisis de componentes principales
humanos
haplotipos
ictiosis
FPGMX
CHUS
CHUVI
IDIS
title_short Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
title_full Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
title_fullStr Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
title_full_unstemmed Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
title_sort Biogeographical origin and timing of the founder ichthyosis TGM1 c.1187G > A mutation in an isolated Ecuadorian population
dc.creator.none.fl_str_mv Esperón Moldes, Uxía Saraiva
Pardo Seco, Jacobo José
Montalván-Suárez, M.
Fachal Vilar, Laura
Ginarte Val, Manuel Javier
Rodríguez Pazos, Laura
Gómez Carballa, Alberto
Moscoso, F.
Ugalde-Noritz, N.
Ordoñez Ugalde, Andrés
Tettamanti-Miranda, D.
Ruiz, J. C.
Salas Ellacuriaga, Antonio
Vega Gliemmo, Ana
author Esperón Moldes, Uxía Saraiva
author_facet Esperón Moldes, Uxía Saraiva
Pardo Seco, Jacobo José
Montalván-Suárez, M.
Fachal Vilar, Laura
Ginarte Val, Manuel Javier
Rodríguez Pazos, Laura
Gómez Carballa, Alberto
Moscoso, F.
Ugalde-Noritz, N.
Ordoñez Ugalde, Andrés
Tettamanti-Miranda, D.
Ruiz, J. C.
Salas Ellacuriaga, Antonio
Vega Gliemmo, Ana
author_role author
author2 Pardo Seco, Jacobo José
Montalván-Suárez, M.
Fachal Vilar, Laura
Ginarte Val, Manuel Javier
Rodríguez Pazos, Laura
Gómez Carballa, Alberto
Moscoso, F.
Ugalde-Noritz, N.
Ordoñez Ugalde, Andrés
Tettamanti-Miranda, D.
Ruiz, J. C.
Salas Ellacuriaga, Antonio
Vega Gliemmo, Ana
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
dc.subject.none.fl_str_mv Humans
Transglutaminases
Ichthyosis
Haplotypes
Principal Component Analysis
Tandem Repeat Sequences
Genotype
transglutaminasas
genotipo
secuencias repetidas en tándem
análisis de componentes principales
humanos
haplotipos
ictiosis
FPGMX
CHUS
CHUVI
IDIS
topic Humans
Transglutaminases
Ichthyosis
Haplotypes
Principal Component Analysis
Tandem Repeat Sequences
Genotype
transglutaminasas
genotipo
secuencias repetidas en tándem
análisis de componentes principales
humanos
haplotipos
ictiosis
FPGMX
CHUS
CHUVI
IDIS
description An unusually high frequency of the lamellar ichthyosis TGM1 mutation, c.1187G > A, has been observed in the Ecuadorian province of Manabi. Recently, the same mutation has been detected in a Galician patient (Northwest of Spain). By analyzing patterns of genetic variation around this mutation in Ecuadorian patients and population matched controls, we were able to estimate the age of c.1187G > A and the time to their most recent common ancestor (TMRCA) of c.1187G > A Ecuadorian carriers. While the estimated mutation age is 41 generations ago (~1,025 years ago [ya]), the TMRCA of Ecuadorian c.1187G > A carrier haplotypes dates to just 17 generations (~425 ya). Probabilistic-based inferences of local ancestry allowed us to infer a most likely European origin of a few (16% to 30%) Ecuadorian haplotypes carrying this mutation. In addition, inferences on demographic historical changes based on c.1187G > A Ecuadorian carrier haplotypes estimated an exponential population growth starting ~20 generations, compatible with a recent founder effect occurring in Manabi. Two main hypotheses can be considered for the origin of c.1187G > A: (i) the mutation could have arisen in Spain >1,000 ya (being Galicia the possible homeland) and then carried to Ecuador by Spaniards in colonial times ~400 ya, and (ii) two independent mutational events originated this mutation in Ecuador and Galicia. The geographic and cultural characteristics of Manabi could have favored a founder effect that explains the high prevalence of TGM1 c.1187G > A in this region.
publishDate 2019
dc.date.none.fl_str_mv 2019
dc.type.none.fl_str_mv info:eu-repo/semantics/article
format article
dc.identifier.none.fl_str_mv https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6509209/pdf/41598_2019_Article_43133.pdf
https://www.ncbi.nlm.nih.gov/pubmed/31073126
http://hdl.handle.net/20.500.11940/15761
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6509209/pdf/41598_2019_Article_43133.pdf
https://www.ncbi.nlm.nih.gov/pubmed/31073126
http://hdl.handle.net/20.500.11940/15761
dc.language.none.fl_str_mv Inglés
language_invalid_str_mv Inglés
dc.rights.none.fl_str_mv http://creativecommons.org/licenses/by/4.0/
info:eu-repo/semantics/openAccess
rights_invalid_str_mv http://creativecommons.org/licenses/by/4.0/
eu_rights_str_mv openAccess
dc.source.none.fl_str_mv reponame:RUNA. Repositorio da Consellería de Sanidade e Sergas
instname:Servizo Galego de Saúde (SERGAS)
instname_str Servizo Galego de Saúde (SERGAS)
reponame_str RUNA. Repositorio da Consellería de Sanidade e Sergas
collection RUNA. Repositorio da Consellería de Sanidade e Sergas
repository.name.fl_str_mv
repository.mail.fl_str_mv
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